Clinical experience and diagnostic algorithm of vulval Crohn's disease

Publication date

2017-07-01

Authors

Boxhoorn, Lotte
Stoof, Tom J.
De Meij, Tim
Hoentjen, Frank
Oldenburg, BasISNI 0000000387307453
Bouma, Gerd
Löwenberg, Mark
Van Bodegraven, Adriaan A.
De Boer, Nanne K.H.
On behalf of the Dutch Initiative on Crohn and Colitis

Editors

Advisors

Supervisors

Document Type

Article

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License

taverne

Abstract

Background and aim: Vulval Crohn's disease (VCD) is a rare extraintestinal cutaneous manifestation of Crohn's disease. No consensus on the diagnostic workup and therapeutic management of this condition has been provided in the current literature. Patients and methods: Retrospective, multicentre descriptive case series of female patients diagnosed and treated with VCD. By chart review, data on initial symptoms, clinical courses, histologic findings and therapeutic management were collected. Results: Fifteen female patients with a median age of 28 years (interquartile range: 28-44 years) suffering from Crohn's disease of the ileum (27%), colon (33%) and ileocolon (40%) were included. VCD manifested most frequently with vulval swelling (93%), pain (80%) and erythema (73%). Histologic analysis demonstrated granulomatous inflammation in 78% and a mixed inflammatory cell infiltrate in 67% of cases. In eight (53%) cases, topical therapy resulted in temporary reduction of vulval symptoms. Combotreatment with immunosuppressive agents and tumour necrosis factor α inhibitors was the most effective second-line therapy: five (33%) patients achieved sustained clinical remission with this therapeutic strategy. Conclusion: The diagnostic workup of VCD is challenging and should be approached in a multidisciplinary manner. Histopathologic analysis of the vulva supports the diagnosis. Topical therapy and systemic treatment with immunosuppressive agents and tumour necrosis factor α inhibitors are advised to treat this condition.

Keywords

Crohn's disease, extraintestinal manifestation, infliximab, vulva, Taverne, Hepatology, Gastroenterology, Journal Article

Citation

Boxhoorn, L, Stoof, T J, De Meij, T, Hoentjen, F, Oldenburg, B, Bouma, G, Löwenberg, M, Van Bodegraven, A A, De Boer, N K H & On behalf of the Dutch Initiative on Crohn and Colitis 2017, 'Clinical experience and diagnostic algorithm of vulval Crohn's disease', European Journal of Gastroenterology and Hepatology, vol. 29, no. 7, pp. 838-843. https://doi.org/10.1097/MEG.0000000000000879