Ubiquitylation of the ER-Shaping Protein Lunapark via the CRL3KLHL12 Ubiquitin Ligase Complex

Publication date

2020-05-19

Authors

Yuniati, Laurensia
Lauriola, Angela
Gerritsen, Manouk
Abreu, Susana
Ni, Eric
Tesoriero, Chiara
Onireti, Jacob O.
Low, Teck Yew
Heck, Albert J.R.
Vettori, Andrea

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Advisors

Supervisors

Document Type

Article

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Abstract

Yuniati et al. perform a proteomic screen to identify E3 substrates that are ubiquitylated at cellular membranes and find that the ER-shaping protein Lunapark is ubiquitylated by the CRL3KLHL12 ubiquitin ligase. They show that Lunapark binds mTORC1 and affects its activity, and defects in Lunapark ubiquitylation lead to neurodevelopmental defects.

Keywords

cullin-RING ligases, endoplasmic reticulum, ER three-way junction, Lunapark, lysosome, mTORC1, ubiquitin, General Biochemistry,Genetics and Molecular Biology

Citation

Yuniati, L, Lauriola, A, Gerritsen, M, Abreu, S, Ni, E, Tesoriero, C, Onireti, J O, Low, T Y, Heck, A J R, Vettori, A, Cardozo, T & Guardavaccaro, D 2020, 'Ubiquitylation of the ER-Shaping Protein Lunapark via the CRL3 KLHL12 Ubiquitin Ligase Complex', Cell Reports, vol. 31, no. 7, 107664, pp. 1-20. https://doi.org/10.1016/j.celrep.2020.107664