A case series of PLS patients with frontotemporal dementia and overview of the literature

Publication date

2017-10-02

Authors

de Vries, Bálint S.
Rustemeijer, Laura M.M.
van der Kooi, Anneke J.
Raaphorst, Joost
Schröder, Carin D.
Nijboer, Tanja C WISNI 0000000390969706
Hendrikse, Jeroen
Veldink, Jan H.
van den Berg, Leonard H.
van Es, M.A.

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Document Type

Article
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Abstract

Objective: Primary lateral sclerosis (PLS) is a rare form of motor neuron disease characterised by UMN degeneration leading to slowly progressive spasticity. Whether it is a separate disease or a subtype of ALS has been debated. In ALS comorbid frontotemporal dementia (FTD) is frequently seen (±15%). However, cognitive and behavioural changes are generally not considered to be a part of PLS. Methods: To report the clinical findings and frequency of PLS patients that developed FTD in a referral-based cohort and provide an overview of the literature. Results: In our cohort six out of 181 (3.3%) PLS patients developed FTD. In the literature a few cases of PLS with FTD have been reported and only a limited number of small studies have investigated cognition in PLS. However, when these studies are summarised a pattern emerges with FTD diagnoses in ±2% and frontotemporal impairment in 22% of patients. Conclusions: These findings suggest that PLS is part of the FTD-MND continuum and would favour viewing it as a subtype of ALS. It is, however, not a restricted (isolated UMN involvement) phenotype.

Keywords

cognition, dementia, frontotemporal dementia, Primary lateral sclerosis, Neurology, Clinical Neurology

Citation

de Vries, B S, Rustemeijer, L M M, van der Kooi, A J, Raaphorst, J, Schröder, C D, Nijboer, T C W, Hendrikse, J, Veldink, J H, van den Berg, L H & van Es, M A 2017, 'A case series of PLS patients with frontotemporal dementia and overview of the literature', Amyotrophic Lateral Sclerosis and Frontotemporal Degeneration, vol. 18, no. 7-8, pp. 534-548. https://doi.org/10.1080/21678421.2017.1354996